Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003105665 | SCV003792476 | pathogenic | Primary pulmonary hypertension | 2022-07-17 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the BMPR2 protein in which other variant(s) (p.Cys420Tyr) have been determined to be pathogenic (PMID: 15146475, 21737554, 21801371, 27453251; Invitae). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. This variant has not been reported in the literature in individuals affected with BMPR2-related conditions. This variant is a gross deletion of the genomic region encompassing exon(s) 7-12 of the BMPR2 gene. While this deletion is not anticipated to lead to nonsense mediated decay, it is expected to disrupt the C-terminus of the protein. |