Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001032806 | SCV001196113 | likely pathogenic | Pulmonary hypertension, primary, 1 | 2019-05-07 | criteria provided, single submitter | clinical testing | This variant is an in-frame deletion of the genomic region encompassing exons 8-9 of the BMPR2 gene. It preserves the integrity of the reading frame. A similar deletion of exons 8-9 has been reported in an individual affected with pulmonary arterial hypertension (PMID: 16429403). This variant disrupts the p.Cys420 amino acid residue in BMPR2. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 15146475, 21737554, 21801371, 27453251). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
Labcorp Genetics |
RCV001378022 | SCV001575498 | likely pathogenic | Primary pulmonary hypertension | 2021-08-04 | criteria provided, single submitter | clinical testing | This variant is a gross deletion of the genomic region encompassing exon(s) 8-9 of the BMPR2 gene. This variant would be expected to be in-frame, preserving the integrity of the reading frame. A similar copy number variant has been observed in individual(s) with pulmonary arterial hypertension (PMID: 16429403). This variant disrupts the p.Cys420 amino acid residue in BMPR2. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 15146475, 21737554, 21801371, 27453251). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |