Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000817280 | SCV000957830 | pathogenic | Chuvash polycythemia; Von Hippel-Lindau syndrome | 2022-09-03 | criteria provided, single submitter | clinical testing | This variant is a gross deletion of the genomic region encompassing exon(s) 2 of the VHL gene. This variant would be expected to be in-frame, preserving the integrity of the reading frame. A similar copy number variant has been observed in individual(s) with von Hippel-Lindau disease (PMID: 12114495, 16884328, 19280651, 19764026). Algorithms developed to predict the effect of variants on protein structure and function are not available or were not evaluated for this variant. Experimental studies have shown that a similar copy number variant affects VHL function (PMID: 11024059). The region of the VHL gene that includes exon(s) 2 has been determined to be clinically significant (PMID: 12114495, 16884328, 19280651, 19764026). Therefore, deletions that encompass that region are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |