Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000456791 | SCV000564072 | pathogenic | Chuvash polycythemia; Von Hippel-Lindau syndrome | 2016-09-03 | criteria provided, single submitter | clinical testing | This variant is a gross deletion of the genomic region encompassing exon 2 of the VHL gene. This leads to an in-frame deletion, preserving the integrity of the reading frame. Deletions of exon 2 have been reported in numerous individuals and families affected with von Hippel-Lindau disease (PMID: 19764026, 19280651, 16884328, 12114495). Experimental studies have shown that deletion of exon 2 leads to expression of a stable VHL protein lacking 41 amino acid residues. This region encodes for the beta-domain of the VHL protein that is essential for proper protein function (PMID: 11024059). For these reasons, this variant has been classified as Pathogenic. |