Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004766527 | SCV005381223 | pathogenic | Cohen syndrome | 2024-08-07 | criteria provided, single submitter | clinical testing | Variant summary: The variant involves the deletion of exons 32-41 in the VPS13B gene. A presumed nomenclature of c.(5024+1_5025-1)_(7504+1_7505-1)del has been designated for the purposes of this classification. This Copy Number Variant (CNV) is expected to alter the reading frame and predicted to result in a truncation or absence of the encoded protein due to nonsense mediated decay (NMD). The variant was absent in 21694 control chromosomes. To our knowledge, no occurrence of c.(5024+1_5025-1)_(7504+1_7505-1)del in individuals affected with Cohen Syndrome and no experimental evidence demonstrating its impact on protein function have been reported. No submitters have cited clinical-significance assessments for this variant to ClinVar. Based on the evidence outlined above, the variant was classified as pathogenic. |