Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV002517660 | SCV003479335 | likely pathogenic | Combined immunodeficiency due to ORAI1 deficiency; Myopathy, tubular aggregate, 2 | 2022-01-07 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with proline, which is neutral and non-polar, at codon 194 of the ORAI1 protein (p.Leu194Pro). This variant is present in population databases (rs782753385, gnomAD 0.005%). This missense change has been observed in individuals with autosomal recessive ORAI1 deficiency (PMID: 20004786, 27066545, 29155098). ClinVar contains an entry for this variant (Variation ID: 192288). Studies have shown that this missense change alters ORAI1 gene expression (PMID: 20004786). In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
OMIM | RCV000172860 | SCV000223836 | pathogenic | Combined immunodeficiency due to ORAI1 deficiency | 2009-12-01 | no assertion criteria provided | literature only |