Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001033621 | SCV001196928 | pathogenic | Developmental and epileptic encephalopathy, 1; Autosomal recessive spinocerebellar ataxia 12 | 2019-10-07 | criteria provided, single submitter | clinical testing | This variant is an out-of-frame deletion of the genomic region encompassing exon 6 of the WWOX gene. This is expected to create a premature translational stop signal and result in an absent or disrupted protein product. A similar deletion of exon 6 has been reported in combination with another WWOX variant in an individual affected with infantile epileptic encephalopathy (PMID: 25411445). ClinVar has an entry for a similar variant (Variant ID: 180247) Loss-of-function variants in WWOX are known to be pathogenic (PMID: 25411445). For these reasons, this variant has been classified as Pathogenic. |