Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000817927 | SCV000958514 | pathogenic | Charcot-Marie-Tooth disease, type I | 2019-08-06 | criteria provided, single submitter | clinical testing | This variant is a gross duplication of the genomic region encompassing exons 2-5 of the PMP22 gene. This assay only includes exons 2-5 of PMP22, which covers the entire coding sequence. Therefore, it is assumed that the entire gene is duplicated. Duplications of the region on chromosome 17p11.2 which contain the PMP22 gene cause Charcot-Marie-Tooth type 1A (CMT1A) (PMID: 1677316, 1822787). These reported duplications have been shown to lead to increased gene dosage as the functional defect in patients with CMT1A (PMID: 1303230). For these reasons, this variant has been classified as Pathogenic. |