Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Women's Health and Genetics/Laboratory Corporation of America, |
RCV002271894 | SCV002556091 | likely pathogenic | Pontoneocerebellar hypoplasia | 2022-06-02 | criteria provided, single submitter | clinical testing | Variant summary: The variant identified by MLPA or other technology involves the deletion of the whole VPS53 gene. A presumed nomenclature of c.(?_-148)_(*10461_?)del has been designated for the purposes of this classification. The variant was absent in 21694 control chromosomes. To our knowledge, no occurrence of c.(?_-148)_(*10461_?)del in individuals affected with Pontocerebellar Hypoplasia, Type 2E and no experimental evidence demonstrating its impact on protein function have been reported. No clinical diagnostic laboratories have submitted clinical-significance assessments for this variant to ClinVar after 2014. Based on the evidence outlined above, the variant was classified as likely pathogenic. |