Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
The Central Laboratory of Birth Defects Prevention and Control, |
RCV004768480 | SCV005382013 | uncertain significance | Hereditary factor VIII deficiency disease | 2024-09-30 | criteria provided, single submitter | clinical testing | Variant summary: The CNV identified by Oxford Nanopore sequencing and optical genome mapping involves 87.56Kb duplication, including a partial int22h3 and TMLHE exon 2-8. Although exact breakpoints of this duplication are not known, the CNV inserted int22h1 of the F8 gene and expected to result in isolation of F8 gene, a known mechanism of disease (PMID: 30088696). No submitters have reported clinical-significance assessments for this CNV to ClinVar. According to the ACMG, the CNV of F8 is a variant of uncertain significance (1A, 2I (Scoring: 0.3), 3A, 5D(Scoring: 0.45))(PMID: 31690835). |