Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000185682 | SCV000238603 | uncertain significance | not provided | 2016-07-27 | criteria provided, single submitter | clinical testing | The S161G variant has been reported in a symptomatic patient with SCAD deficiency (Gregersen et al. 2008). The S161G variant was not observed in approximately 6500 individuals of European and African American ancestry in the NHLBI Exome Sequencing Project, indicating it is not a common benign variant in these populations. The S161G variant is a non-conservative amino acid substitution, which is likely to impact secondary protein structure as these residues differ in polarity, charge, size and/or other properties. This substitution occurs at a position that is conserved across species. In silico analysis predicts this variant is probably damaging to the protein structure/function. In summary, based on the currently available information, it is unclear whether the S161G variant is a pathogenic variant or a rare benign variant. |
Labcorp Genetics |
RCV001305034 | SCV001494346 | uncertain significance | Deficiency of butyryl-CoA dehydrogenase | 2022-02-01 | criteria provided, single submitter | clinical testing | This sequence change replaces serine, which is neutral and polar, with glycine, which is neutral and non-polar, at codon 161 of the ACADS protein (p.Ser161Gly). This variant is present in population databases (rs755856935, gnomAD 0.003%). This variant has not been reported in the literature in individuals affected with ACADS-related conditions. ClinVar contains an entry for this variant (Variation ID: 203553). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Benign"; Align-GVGD: "Class C55"). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Genome- |
RCV001305034 | SCV002033267 | uncertain significance | Deficiency of butyryl-CoA dehydrogenase | 2021-11-07 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV001305034 | SCV002784497 | uncertain significance | Deficiency of butyryl-CoA dehydrogenase | 2021-09-10 | criteria provided, single submitter | clinical testing |