Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001477684 | SCV003936887 | likely benign | Very long chain acyl-CoA dehydrogenase deficiency | 2023-06-27 | reviewed by expert panel | curation | The c.822C>T variant is a synonymous (silent) variant (p.Ala274=) that is not predicted by SpliceAI, NNSPLICE, or MaxEntScan to impact splicing. In addition, it occurs at a nucleotide that is not conserved as shown by 100 vertebrate Basewise Conservation by PhyloP track in the UCSC genome browser (BP4, BP7). This highest population minor allele frequency in gnomAD v2.1.1 is 0.0003185 in the European (Finnish) population, which is lower than the ClinGen ACADVL Variant Curation Expert Panel threshold (<0.001) for PM2_Supporting; however, this is not considered conflicting evidence with BP4 and BP7. In summary, this variant meets the criteria to be classified as likely benign for autosomal recessive very long chain acyl-CoA dehydrogenase (VLCAD) deficiency based on the ACMG/AMP criteria applied, as specified by the ClinGen ACADVL Variant Curation Expert Panel: BP4, BP7 (ACADVL VCEP specifications version 1; approved November 8, 2021) |
Prevention |
RCV000249127 | SCV000301530 | likely benign | not specified | criteria provided, single submitter | clinical testing | ||
Labcorp Genetics |
RCV001477684 | SCV001681930 | likely benign | Very long chain acyl-CoA dehydrogenase deficiency | 2023-06-25 | criteria provided, single submitter | clinical testing |