Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV002132655 | SCV005375381 | uncertain significance | Severe combined immunodeficiency, autosomal recessive, T cell-negative, B cell-negative, NK cell-negative, due to adenosine deaminase deficiency | 2024-04-23 | reviewed by expert panel | curation | The c.930G>A (NM_000022.4) variant in ADA is a missense variant predicted to cause substitution of Methionine by Isoleucine at amino acid 310 (p.Met310Ile). The filtering allele frequency (the upper threshold of the 95% CI of 37/74916 alleles) of the c.930G>A variant in ADA is 0.0003682 for African/African American chromosomes by gnomAD v4, which is lower than the ClinGen SCID VCEP threshold for BS1 (>0.00161) and BA1 (>0.00721) but higher than the threshold (<0.0001742) for PM2_Supporting (BS1 not met, BA1 not met, PM2_Supporting not met). No homozygotes have been observed in gnomAD. To our knowledge, this variant has not been reported in the literature in individuals affected with ADA-related conditions or in functional studies. Due to insufficient evidence, this variant is classified as a variant of uncertain significance for autosomal recessive SCID based on ACMG/AMP criteria applied, as specified by the ClinGen SCID VCEP (specification version 1.0): No criteria were applied. |
Labcorp Genetics |
RCV002132655 | SCV002435236 | likely benign | Severe combined immunodeficiency, autosomal recessive, T cell-negative, B cell-negative, NK cell-negative, due to adenosine deaminase deficiency | 2024-10-30 | criteria provided, single submitter | clinical testing |