Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000665054 | SCV000789113 | likely pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2017-01-11 | criteria provided, single submitter | clinical testing | |
Invitae | RCV000665054 | SCV000937162 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2023-10-03 | criteria provided, single submitter | clinical testing | This sequence change replaces leucine, which is neutral and non-polar, with proline, which is neutral and non-polar, at codon 31 of the SGCA protein (p.Leu31Pro). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individuals with autosomal recessive limb-girdle muscular dystrophy (PMID: 9032047, 12566530, 18285821, 29351619). ClinVar contains an entry for this variant (Variation ID: 550333). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt SGCA protein function. Experimental studies have shown that this missense change affects SGCA function (PMID: 22095924, 29351619). For these reasons, this variant has been classified as Pathogenic. |
Undiagnosed Diseases Network, |
RCV000665054 | SCV001432771 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2020-06-30 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV000665054 | SCV003931628 | likely pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2023-02-08 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000665054 | SCV004203177 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2024-02-27 | criteria provided, single submitter | clinical testing | |
Revvity Omics, |
RCV000665054 | SCV004238349 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2D | 2023-02-14 | criteria provided, single submitter | clinical testing |