Total submissions: 9
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Mendelics | RCV000186278 | SCV001136273 | pathogenic | Primary hyperoxaluria, type I | 2019-05-28 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001383728 | SCV001582980 | pathogenic | not provided | 2024-01-13 | criteria provided, single submitter | clinical testing | This sequence change replaces arginine, which is basic and polar, with histidine, which is basic and polar, at codon 36 of the AGXT protein (p.Arg36His). This variant is present in population databases (rs180177162, gnomAD 0.003%). This missense change has been observed in individual(s) with AGXT-related conditions (PMID: 30341509). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 204072). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt AGXT protein function with a positive predictive value of 80%. Experimental studies have shown that this missense change affects AGXT function (PMID: 19479957, 29110180, 30341509). This variant disrupts the p.Arg36 amino acid residue in AGXT. Other variant(s) that disrupt this residue have been determined to be pathogenic (PMID: 15356974, 17495019, 22923379, 24718375, 24988064). This suggests that this residue is clinically significant, and that variants that disrupt this residue are likely to be disease-causing. For these reasons, this variant has been classified as Pathogenic. |
Arcensus | RCV000186278 | SCV002564578 | likely pathogenic | Primary hyperoxaluria, type I | 2013-02-01 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV000186278 | SCV002809718 | likely pathogenic | Primary hyperoxaluria, type I | 2022-03-23 | criteria provided, single submitter | clinical testing | |
Revvity Omics, |
RCV000186278 | SCV003828220 | likely pathogenic | Primary hyperoxaluria, type I | 2021-11-12 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000186278 | SCV004194227 | likely pathogenic | Primary hyperoxaluria, type I | 2024-03-02 | criteria provided, single submitter | clinical testing | |
Ce |
RCV001383728 | SCV005050616 | pathogenic | not provided | 2024-05-01 | criteria provided, single submitter | clinical testing | AGXT: PM3:Strong, PM2, PM5, PP4, PS3:Supporting |
Gene |
RCV001383728 | SCV005333569 | likely pathogenic | not provided | 2024-03-27 | criteria provided, single submitter | clinical testing | Not observed at significant frequency in large population cohorts (gnomAD); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 34426522, 31589614, 30341509, 19479957, 34493867, 37464296, 36185032, 15356974, 17495019, 24988064, 37139236, 29110180) |
Clinical Biochemistry Laboratory, |
RCV000186278 | SCV000239604 | pathogenic | Primary hyperoxaluria, type I | 2014-11-27 | no assertion criteria provided | in vitro |