Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Institute of Human Genetics, |
RCV001252970 | SCV001428450 | pathogenic | Adrenoleukodystrophy | 2019-05-06 | criteria provided, single submitter | clinical testing | This variant was identified as hemizygous |
3billion | RCV001252970 | SCV003841267 | uncertain significance | Adrenoleukodystrophy | 2023-02-23 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Missense changes are a common disease-causing mechanism. In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.96; 3Cnet: 0.98). Same nucleotide change resulting in same amino acid change has been previously reported to be associated with ABCD1 related disorder (ClinVar ID: VCV000975856 / PMID: 12402273). However, the evidence of pathogenicity is insufficient at this time. Therefore, this variant is classified as VUS according to the recommendation of ACMG/AMP guideline. |