Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Laboratory of Diagnosis and Therapy of Lysosomal Disorders, |
RCV000677606 | SCV000803123 | likely pathogenic | Mucopolysaccharidosis type 6 | 2018-01-01 | criteria provided, single submitter | curation | In vitro functional studies supportive of a damaging effect on the gene product (low to no ARSB activity in homozygotes; PS3); Absent from GnomAD (PM2) |
Labcorp Genetics |
RCV000677606 | SCV002232247 | pathogenic | Mucopolysaccharidosis type 6 | 2023-09-10 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (gnomAD no frequency). For these reasons, this variant has been classified as Pathogenic. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ARSB protein function. ClinVar contains an entry for this variant (Variation ID: 559823). This missense change has been observed in individuals with mucopolysaccharidosis type VI (PMID: 18486607, 25190157, 25654180). This sequence change replaces glycine, which is neutral and non-polar, with glutamic acid, which is acidic and polar, at codon 303 of the ARSB protein (p.Gly303Glu). |
Baylor Genetics | RCV000677606 | SCV004209336 | likely pathogenic | Mucopolysaccharidosis type 6 | 2023-06-22 | criteria provided, single submitter | clinical testing |