Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000211672 | SCV000799166 | uncertain significance | Argininosuccinate lyase deficiency | 2018-04-09 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000211672 | SCV002231187 | pathogenic | Argininosuccinate lyase deficiency | 2023-10-28 | criteria provided, single submitter | clinical testing | This sequence change replaces methionine, which is neutral and non-polar, with threonine, which is neutral and polar, at codon 360 of the ASL protein (p.Met360Thr). This variant is not present in population databases (gnomAD no frequency). This missense change has been observed in individual(s) with argininosuccinate lyase deficiency (Invitae). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. ClinVar contains an entry for this variant (Variation ID: 226414). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is expected to disrupt ASL protein function with a positive predictive value of 95%. Experimental studies have shown that this missense change affects ASL function (PMID: 11747433). For these reasons, this variant has been classified as Pathogenic. |
Genomic Research Center, |
RCV000211672 | SCV000268690 | pathogenic | Argininosuccinate lyase deficiency | 2016-05-09 | no assertion criteria provided | clinical testing |