Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV003050627 | SCV003445358 | pathogenic | Menkes kinky-hair syndrome; Cutis laxa, X-linked; X-linked distal spinal muscular atrophy type 3 | 2022-02-02 | criteria provided, single submitter | clinical testing | This premature translational stop signal has been observed in individual(s) with Menkes disease (PMID: 18256395). For these reasons, this variant has been classified as Pathogenic. This variant is not present in population databases (gnomAD no frequency). This sequence change creates a premature translational stop signal (p.Gln1385*) in the ATP7A gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in ATP7A are known to be pathogenic (PMID: 11241493, 20652413). |
Inherited Neuropathy Consortium Ii, |
RCV003312071 | SCV004011865 | uncertain significance | Menkes kinky-hair syndrome | 2016-01-06 | no assertion criteria provided | literature only |