Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Fulgent Genetics, |
RCV001007657 | SCV005640465 | pathogenic | Bloom syndrome | 2024-01-30 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001007657 | SCV005697882 | pathogenic | Bloom syndrome | 2024-10-23 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Gln937*) in the BLM gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in BLM are known to be pathogenic (PMID: 17407155). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with clinical features of Bloom syndrome (PMID: 31696992). ClinVar contains an entry for this variant (Variation ID: 694003). For these reasons, this variant has been classified as Pathogenic. |
Institut de Recherche Interdisciplinaire en Biologie Humaine et Moleculaire, |
RCV001007657 | SCV000998519 | pathogenic | Bloom syndrome | no assertion criteria provided | clinical testing |