Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000804167 | SCV000944063 | uncertain significance | Bloom syndrome | 2024-11-15 | criteria provided, single submitter | clinical testing | This sequence change replaces alanine, which is neutral and non-polar, with glycine, which is neutral and non-polar, at codon 1124 of the BLM protein (p.Ala1124Gly). This variant is present in population databases (rs751765688, gnomAD 0.02%). This variant has not been reported in the literature in individuals affected with BLM-related conditions. ClinVar contains an entry for this variant (Variation ID: 649273). Invitae Evidence Modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) has been performed for this missense variant. However, the output from this modeling did not meet the statistical confidence thresholds required to predict the impact of this variant on BLM protein function. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV002453784 | SCV002614401 | uncertain significance | Hereditary cancer-predisposing syndrome | 2024-01-13 | criteria provided, single submitter | clinical testing | The p.A1124G variant (also known as c.3371C>G), located in coding exon 17 of the BLM gene, results from a C to G substitution at nucleotide position 3371. The alanine at codon 1124 is replaced by glycine, an amino acid with similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, the in silico prediction for this alteration is inconclusive. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
Natera, |
RCV000804167 | SCV002090559 | uncertain significance | Bloom syndrome | 2018-11-13 | no assertion criteria provided | clinical testing |