Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000012100 | SCV002228895 | pathogenic | X-linked agammaglobulinemia with growth hormone deficiency | 2022-08-16 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Studies have shown that this variant alters mRNA splicing and is expected to lead to the loss of protein expression (PMID: 8013627). ClinVar contains an entry for this variant (Variation ID: 11347). This variant is also known as 1882+5G>A and IVS17+5G>A. This variant has been observed in individuals with agammaglobulinemia (PMID: 8013627, 14974089, 29709555, 30240888). This variant is not present in population databases (gnomAD no frequency). This sequence change falls in intron 17 of the BTK gene. It does not directly change the encoded amino acid sequence of the BTK protein. RNA analysis indicates that this variant induces altered splicing and may result in an absent or disrupted protein product. |
OMIM | RCV000012100 | SCV000032334 | pathogenic | X-linked agammaglobulinemia with growth hormone deficiency | 1994-06-13 | no assertion criteria provided | literature only |