Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001776432 | SCV002012990 | uncertain significance | not provided | 2019-11-14 | criteria provided, single submitter | clinical testing | In silico analysis, which includes protein predictors and evolutionary conservation, supports a deleterious effect; Not observed in large population cohorts (Lek et al., 2016); Cultured myotubules from an affected individual demonstrated reduced KCL-induced Ca2+ release, suggesting a defect in excitation-contraction coupling; however studies were not completed in a heterologous expression system (Schartner et al., 2017); This variant is associated with the following publications: (PMID: 28012042) |
OMIM | RCV003222344 | SCV003841108 | pathogenic | Congenital myopathy 18 | 2024-07-16 | no assertion criteria provided | literature only |