Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
3billion, |
RCV002283891 | SCV002573062 | pathogenic | Chédiak-Higashi syndrome | 2022-09-01 | criteria provided, single submitter | clinical testing | The variant is not observed in the gnomAD v2.1.1 dataset. Stop-gained (nonsense) is predicted to result in a loss or disruption of normal protein function through nonsense-mediated decay (NMD) or protein truncation. Multiple pathogenic variants are reported downstream of the variant. The variant has been reported to be associated with LYST-related disorder (PMID: 30815890). Therefore, this variant is classified as Pathogenic according to the recommendation of ACMG/AMP guideline. |
Fulgent Genetics, |
RCV002283891 | SCV005644462 | likely pathogenic | Chédiak-Higashi syndrome | 2024-05-02 | criteria provided, single submitter | clinical testing |