Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Medical Genetics, |
RCV001089906 | SCV001245139 | likely pathogenic | Autosomal recessive Alport syndrome | 2020-03-11 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV002554801 | SCV003302667 | likely pathogenic | not provided | 2023-08-05 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. ClinVar contains an entry for this variant (Variation ID: 870354). This variant has been observed in individual(s) with Alport syndrome (PMID: 33369211). This variant is not present in population databases (gnomAD no frequency). This variant results in the deletion of part of exon 31 of the COL4A3 gene. It is expected to disrupt RNA splicing. Variants that disrupt the donor or acceptor splice site typically lead to a loss of protein function (PMID: 16199547), and loss-of-function variants in COL4A3 are known to be pathogenic (PMID: 8956999, 24854265, 26809805, 27281700). |