Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001851641 | SCV002240090 | pathogenic | Achondrogenesis, type IB; Atelosteogenesis type II; Multiple epiphyseal dysplasia type 4; Diastrophic dysplasia | 2023-06-08 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (gnomAD no frequency). For these reasons, this variant has been classified as Pathogenic. Experimental studies have shown that this missense change affects SLC26A2 function (PMID: 11448940). Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) has been performed at Invitae for this missense variant, however the output from this modeling did not meet the statistical confidence thresholds required to predict the impact of this variant on SLC26A2 protein function. ClinVar contains an entry for this variant (Variation ID: 4093). This missense change has been observed in individual(s) with diastrophic dysplasia (PMID: 8528239, 9342225, 21155763). This sequence change replaces asparagine, which is neutral and polar, with aspartic acid, which is acidic and polar, at codon 425 of the SLC26A2 protein (p.Asn425Asp). |
Fulgent Genetics, |
RCV001851641 | SCV002780742 | likely pathogenic | Achondrogenesis, type IB; Atelosteogenesis type II; Multiple epiphyseal dysplasia type 4; Diastrophic dysplasia | 2021-08-23 | criteria provided, single submitter | clinical testing | |
Baylor Genetics | RCV000023569 | SCV005056821 | likely pathogenic | Achondrogenesis, type IB | 2024-01-08 | criteria provided, single submitter | clinical testing | |
OMIM | RCV000023569 | SCV000044860 | pathogenic | Achondrogenesis, type IB | 1996-01-01 | no assertion criteria provided | literature only | |
Gene |
RCV000055757 | SCV000086697 | not provided | Diastrophic dysplasia | no assertion provided | literature only |