Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001770598 | SCV001993828 | uncertain significance | not provided | 2019-05-15 | criteria provided, single submitter | clinical testing | Not observed at a significant frequency in large population cohorts (Lek et al., 2016); Has not been previously published as pathogenic or benign to our knowledge; This variant is associated with the following publications: (PMID: 29641532) |
Fulgent Genetics, |
RCV002477939 | SCV002784143 | uncertain significance | Xeroderma pigmentosum, group G; Cerebrooculofacioskeletal syndrome 3 | 2021-08-24 | criteria provided, single submitter | clinical testing | |
Invitae | RCV001770598 | SCV004653595 | uncertain significance | not provided | 2023-06-14 | criteria provided, single submitter | clinical testing | ClinVar contains an entry for this variant (Variation ID: 1305806). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be disruptive. This variant has not been reported in the literature in individuals affected with ERCC5-related conditions. This variant is present in population databases (rs759962943, gnomAD 0.003%). This sequence change replaces alanine, which is neutral and non-polar, with serine, which is neutral and polar, at codon 347 of the ERCC5 protein (p.Ala347Ser). |