Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ambry Genetics | RCV001267058 | SCV001445239 | pathogenic | Inborn genetic diseases | 2017-08-31 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV005094275 | SCV005835398 | pathogenic | Multiple congenital exostosis | 2024-10-07 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Trp529*) in the EXT1 gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in EXT1 are known to be pathogenic (PMID: 10679937, 11391482, 19810120). This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with multiple osteochondromas (PMID: 17041877). ClinVar contains an entry for this variant (Variation ID: 985903). For these reasons, this variant has been classified as Pathogenic. |