Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000803549 | SCV000943427 | pathogenic | Multiple congenital exostosis | 2018-12-09 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (ExAC no frequency). For these reasons, this variant has been classified as Pathogenic. Loss-of-function variants in EXT1 are known to be pathogenic (PMID: 10679937, 11391482, 19810120). A different variant (c.1911C>G) giving rise to the same protein effect observed here (p.Tyr637*) has been determined to be pathogenic (PMID: 29529714). This variant has been observed in individuals with multiple osteochondromas (PMID: 29126381, Invitae). This sequence change creates a premature translational stop signal (p.Tyr637*) in the EXT1 gene. It is expected to result in an absent or disrupted protein product. |
Department of Laboratory Medicine, |
RCV000803549 | SCV001167351 | pathogenic | Multiple congenital exostosis | criteria provided, single submitter | research |