Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
NIHR Bioresource Rare Diseases, |
RCV000852189 | SCV000899862 | pathogenic | Hereditary factor IX deficiency disease | 2019-02-01 | criteria provided, single submitter | research | |
ARUP Laboratories, |
RCV000010810 | SCV002047742 | pathogenic | Hereditary factor VIII deficiency disease | 2021-05-01 | criteria provided, single submitter | clinical testing | The F8 c.6683G>A;p.Arg2228Gln variant (rs137852358), also known as Arg2209Gln, has been described in the literature in individuals with hemophilia with inconsistent severity classifications (see link and references therein). The variant is reported in ClinVar (Variation ID: 10098) but is absent from the Genome Aggregation Database, indicating is not a common polymorphism. The arginine at codon 2228 is highly conserved, and computational analyses predict that this variant is deleterious (REVEL:0.94). Taken together, this variant is considered pathogenic. References: Link to F8 database: http://www.factorviii-db.org/newstructure.php?aa_first=Arg&mut_id=1705&aa_last=Gln&variable=1705&hash=3361dcd5af0c49e04a7cc11718a9419c |
OMIM | RCV000010810 | SCV000031037 | pathogenic | Hereditary factor VIII deficiency disease | 1990-02-01 | no assertion criteria provided | literature only |