Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
ARUP Laboratories, |
RCV001812588 | SCV002049751 | pathogenic | not provided | 2021-07-01 | criteria provided, single submitter | clinical testing | The F9 c.839-1G>A variant (rs1439169192) is reported in the literature in multiple individuals affected with severe hemophilia B (see factor VI and references therein). This variant is absent from the Genome Aggregation Database, indicating it is not a common polymorphism. This variant disrupts the canonical splice acceptor site of intron seven, which is likely to negatively impact gene function. Based on available information, this variant is considered to be pathogenic References: Link to Factor VI database: https://f9-db.eahad.org/index.php |
Labcorp Genetics |
RCV003772215 | SCV004571523 | pathogenic | Hereditary factor IX deficiency disease; Thrombophilia, X-linked, due to factor 9 defect | 2024-01-15 | criteria provided, single submitter | clinical testing | This sequence change affects an acceptor splice site in intron 7 of the F9 gene. While this variant is not anticipated to result in nonsense mediated decay, it likely alters RNA splicing and results in a disrupted protein product. This variant is not present in population databases (gnomAD no frequency). Disruption of this splice site has been observed in individuals with Hemophilia B (PMID: 2020563, 2212858, 30817051; Invitae). ClinVar contains an entry for this variant (Variation ID: 1331043). Variants that disrupt the consensus splice site are a relatively common cause of aberrant splicing (PMID: 17576681, 9536098). Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may disrupt the consensus splice site. For these reasons, this variant has been classified as Pathogenic. |
OMIM | RCV001815042 | SCV000031563 | pathogenic | Hereditary factor IX deficiency disease | 2013-09-11 | no assertion criteria provided | literature only |