Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001879790 | SCV002311533 | likely pathogenic | Fanconi anemia | 2023-04-07 | criteria provided, single submitter | clinical testing | This sequence change affects a splice site in intron 36 of the FANCA gene. RNA analysis indicates that disruption of this splice site induces altered splicing and may result in an absent or disrupted protein product. This variant is not present in population databases (gnomAD no frequency). Disruption of this splice site has been observed in individual(s) with Fanconi anemia (PMID: 15523645). ClinVar contains an entry for this variant (Variation ID: 974162). Studies have shown that disruption of this splice site results in skipping of exon 37 or deletion of 16 base pairs in exon 37 due to activation of a cryptic splice site and introduces a premature termination codon (PMID: 15523645). The resulting mRNA is expected to undergo nonsense-mediated decay. In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. |
Baylor Genetics | RCV001256407 | SCV004196591 | pathogenic | Fanconi anemia complementation group A | 2023-01-31 | criteria provided, single submitter | clinical testing | |
Leiden Open Variation Database | RCV001256407 | SCV001425853 | pathogenic | Fanconi anemia complementation group A | 2020-02-28 | no assertion criteria provided | curation | Curator: Arleen D. Auerbach. Submitter to LOVD: Arleen D. Auerbach. |