Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000003617 | SCV000798357 | pathogenic | Fanconi anemia complementation group A | 2018-03-07 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001851619 | SCV002189027 | pathogenic | Fanconi anemia | 2023-11-10 | criteria provided, single submitter | clinical testing | This sequence change creates a premature translational stop signal (p.Glu1240Aspfs*36) in the FANCA gene. RNA analysis indicates that this premature translational stop signal induces altered splicing and may result in an absent or disrupted protein product. This variant is not present in population databases (gnomAD no frequency). This premature translational stop signal has been observed in individual(s) with Fanconi anemia (PMID: 15523645, 23067021). ClinVar contains an entry for this variant (Variation ID: 3448). Studies have shown that this premature translational stop signal results in skipping of exon 37 and introduces a premature termination codon (PMID: 15523645). The resulting mRNA is expected to undergo nonsense-mediated decay. For these reasons, this variant has been classified as Pathogenic. |
Baylor Genetics | RCV000003617 | SCV004196563 | pathogenic | Fanconi anemia complementation group A | 2023-03-28 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV001851619 | SCV005185666 | pathogenic | Fanconi anemia | 2024-05-16 | criteria provided, single submitter | clinical testing | Variant summary: FANCA c.3720_3724delAAACA (p.Glu1240AspfsX36) results in a premature termination codon, predicted to cause absence of the protein due to nonsense mediated decay, which is a commonly known mechanism for disease. The variant was absent in 251474 control chromosomes (gnomAD). c.3720_3724delAAACA has been reported in the literature in individuals affected with Fanconi Anemia (e.g. Mori_2019). The following publication has been ascertained in the context of this evaluation (PMID: 30792206). ClinVar contains an entry for this variant (Variation ID: 3448). Based on the evidence outlined above, the variant was classified as pathogenic. |
OMIM | RCV000003617 | SCV000023775 | pathogenic | Fanconi anemia complementation group A | 2004-12-01 | no assertion criteria provided | literature only | |
Leiden Open Variation Database | RCV000003617 | SCV001425860 | pathogenic | Fanconi anemia complementation group A | 2020-02-28 | no assertion criteria provided | curation | Curator: Arleen D. Auerbach. Submitters to LOVD: Arleen D. Auerbach, Myungshin Kim. |