Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV000814307 | SCV000954710 | likely benign | Marfan syndrome; Familial thoracic aortic aneurysm and aortic dissection | 2022-11-15 | criteria provided, single submitter | clinical testing | |
Color Diagnostics, |
RCV001191447 | SCV001359268 | uncertain significance | Familial thoracic aortic aneurysm and aortic dissection | 2023-12-04 | criteria provided, single submitter | clinical testing | This missense variant replaces proline with leucine at codon 404 of the FBN1 protein. Computational prediction tools and conservation analyses are inconclusive regarding the impact of this variant on the protein function. Computational splicing tools suggest that this variant may not impact RNA splicing. To our knowledge, functional assays have not been performed for this variant nor has this variant been reported in individuals affected with cardiovascular disorders in the literature. This variant has been identified in 1/250990 chromosomes in the general population by the Genome Aggregation Database (gnomAD). Available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |
Ambry Genetics | RCV001191447 | SCV002652607 | uncertain significance | Familial thoracic aortic aneurysm and aortic dissection | 2022-05-25 | criteria provided, single submitter | clinical testing | The p.P404L variant (also known as c.1211C>T), located in coding exon 10 of the FBN1 gene, results from a C to T substitution at nucleotide position 1211. The proline at codon 404 is replaced by leucine, an amino acid with similar properties. This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be tolerated by in silico analysis. Since supporting evidence is limited at this time, the clinical significance of this alteration remains unclear. |
All of Us Research Program, |
RCV004803258 | SCV005424924 | uncertain significance | Marfan syndrome | 2024-07-20 | criteria provided, single submitter | clinical testing | This missense variant replaces proline with leucine at codon 404 of the FBN1 protein. Computational prediction tools and conservation analyses are inconclusive regarding the impact of this variant on the protein function. Computational splicing tools suggest that this variant may not impact RNA splicing. To our knowledge, functional assays have not been performed for this variant nor has this variant been reported in individuals affected with cardiovascular disorders in the literature. This variant has been identified in 1/250990 chromosomes in the general population by the Genome Aggregation Database (gnomAD). Available evidence is insufficient to determine the role of this variant in disease conclusively. Therefore, this variant is classified as a Variant of Uncertain Significance. |