Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001302603 | SCV001491817 | uncertain significance | Marfan syndrome; Familial thoracic aortic aneurysm and aortic dissection | 2023-08-17 | criteria provided, single submitter | clinical testing | This variant is not present in population databases (gnomAD no frequency). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Advanced modeling of protein sequence and biophysical properties (such as structural, functional, and spatial information, amino acid conservation, physicochemical variation, residue mobility, and thermodynamic stability) performed at Invitae indicates that this missense variant is not expected to disrupt FBN1 protein function. ClinVar contains an entry for this variant (Variation ID: 1005680). This variant has not been reported in the literature in individuals affected with FBN1-related conditions. This sequence change replaces alanine, which is neutral and non-polar, with threonine, which is neutral and polar, at codon 1271 of the FBN1 protein (p.Ala1271Thr). |
All of Us Research Program, |
RCV004005014 | SCV004839492 | uncertain significance | Marfan syndrome | 2023-12-01 | criteria provided, single submitter | clinical testing | |
Women's Health and Genetics/Laboratory Corporation of America, |
RCV004782699 | SCV005395572 | uncertain significance | not specified | 2024-09-09 | criteria provided, single submitter | clinical testing | Variant summary: FBN1 c.3811G>A (p.Ala1271Thr) results in a non-conservative amino acid change located in the EGF-like domain (IPR000742) of the encoded protein sequence. Three of five in-silico tools predict a benign effect of the variant on protein function. The variant was absent in 251146 control chromosomes. The available data on variant occurrences in the general population are insufficient to allow any conclusion about variant significance. To our knowledge, no occurrence of c.3811G>A in individuals affected with Marfan Syndrome and no experimental evidence demonstrating its impact on protein function have been reported. ClinVar contains an entry for this variant (Variation ID: 1005680). Based on the evidence outlined above, the variant was classified as uncertain significance. |
Prevention |
RCV004727106 | SCV005335763 | uncertain significance | FBN1-related disorder | 2024-04-09 | no assertion criteria provided | clinical testing | The FBN1 c.3811G>A variant is predicted to result in the amino acid substitution p.Ala1271Thr. To our knowledge, this variant has not been reported in the literature or in a large population database, indicating this variant is rare. At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |