Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000181673 | SCV000233976 | pathogenic | not provided | 2014-03-02 | criteria provided, single submitter | clinical testing | Although the c.6722_6725dupACCG variant in the FBN1 gene has not been reported to our knowledge, this variant causes a shift in reading frame starting at codon Arginine 2243, changing it to a Proline, and creating a premature stop codon at position 2 of the new reading frame, denoted p.Arg2243ProfsX2. This variant is expected to result in either an abnormal, truncated protein product or loss of protein from this allele through nonsense-mediated mRNA decay. Other frameshift variants in the FBN1 gene have been reported in association with Marfan syndrome. In summary, c.6722_6725dupACCG in the FBN1 gene is interpreted as a pathogenic variant. |