Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001053248 | SCV001217499 | pathogenic | Glycogen storage disease, type II | 2023-06-22 | criteria provided, single submitter | clinical testing | Disruption of this splice site has been observed in individual(s) with Pompe disease (PMID: 11343339, 18429042). In at least one individual the data is consistent with being in trans (on the opposite chromosome) from a pathogenic variant. For these reasons, this variant has been classified as Pathogenic. Studies have shown that disruption of this splice site results in skipping of exon 9, but is expected to preserve the integrity of the reading-frame (PMID: 11343339). ClinVar contains an entry for this variant (Variation ID: 849313). This variant is not present in population databases (gnomAD no frequency). This sequence change affects a donor splice site in intron 9 of the GAA gene. RNA analysis indicates that disruption of this splice site induces altered splicing and likely results in a shortened protein product. |