Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV001704991 | SCV000241144 | uncertain significance | not provided | 2019-06-03 | criteria provided, single submitter | clinical testing | In silico analysis, which includes protein predictors and evolutionary conservation, supports a deleterious effect; Has not been previously published as pathogenic or benign to our knowledge |
Genetic Services Laboratory, |
RCV000187550 | SCV000247449 | uncertain significance | not specified | 2015-06-22 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001248221 | SCV001421691 | uncertain significance | Cerebral creatine deficiency syndrome | 2021-12-31 | criteria provided, single submitter | clinical testing | This sequence change replaces glycine, which is neutral and non-polar, with serine, which is neutral and polar, at codon 127 of the GAMT protein (p.Gly127Ser). This variant is present in population databases (rs570476209, gnomAD 0.02%). This variant has not been reported in the literature in individuals affected with GAMT-related conditions. ClinVar contains an entry for this variant (Variation ID: 205567). Algorithms developed to predict the effect of missense changes on protein structure and function output the following: SIFT: "Deleterious"; PolyPhen-2: "Benign"; Align-GVGD: "Class C0". The serine amino acid residue is found in multiple mammalian species, which suggests that this missense change does not adversely affect protein function. Algorithms developed to predict the effect of sequence changes on RNA splicing suggest that this variant may create or strengthen a splice site. In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Natera, |
RCV001272272 | SCV001454103 | likely benign | Deficiency of guanidinoacetate methyltransferase | 2020-09-16 | no assertion criteria provided | clinical testing |