Total submissions: 9
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001304040 | SCV001493307 | uncertain significance | not provided | 2024-10-11 | criteria provided, single submitter | clinical testing | This sequence change replaces glutamine, which is neutral and polar, with lysine, which is basic and polar, at codon 400 of the CFH protein (p.Gln400Lys). This variant is present in population databases (rs201671665, gnomAD 0.02%). This missense change has been observed in individual(s) with atypical hemolytic uremic syndrome and age-related macular degeneration (PMID: 22410797, 25814826, 29888403, 34508573). ClinVar contains an entry for this variant (Variation ID: 1006921). An algorithm developed to predict the effect of missense changes on protein structure and function (PolyPhen-2) suggests that this variant is likely to be tolerated. Experimental studies have shown that this missense change does not substantially affect CFH function (PMID: 36445700). In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Baylor Genetics | RCV001332256 | SCV001524513 | uncertain significance | Factor H deficiency | 2020-09-24 | criteria provided, single submitter | clinical testing | This variant was determined to be of uncertain significance according to ACMG Guidelines, 2015 [PMID:25741868]. |
Fulgent Genetics, |
RCV002499567 | SCV002789829 | uncertain significance | Basal laminar drusen; Factor H deficiency; Hemolytic uremic syndrome, atypical, susceptibility to, 1; Age related macular degeneration 4 | 2022-04-13 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003449864 | SCV004180779 | uncertain significance | Hemolytic uremic syndrome, atypical, susceptibility to, 1 | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003449866 | SCV004180780 | uncertain significance | Age related macular degeneration 4 | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV003449865 | SCV004180781 | uncertain significance | Basal laminar drusen | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Genome- |
RCV001332256 | SCV004180782 | uncertain significance | Factor H deficiency | 2023-04-11 | criteria provided, single submitter | clinical testing | |
Diagnostic Laboratory, |
RCV001304040 | SCV001742254 | uncertain significance | not provided | no assertion criteria provided | clinical testing | ||
Clinical Genetics DNA and cytogenetics Diagnostics Lab, |
RCV001304040 | SCV001964200 | uncertain significance | not provided | no assertion criteria provided | clinical testing |