Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001949639 | SCV002238408 | pathogenic | not provided | 2021-09-15 | criteria provided, single submitter | clinical testing | This variant is also known as R389X. This sequence change creates a premature translational stop signal (p.Arg416*) in the INSR gene. It is expected to result in an absent or disrupted protein product. Loss-of-function variants in INSR are known to be pathogenic (PMID: 12023989, 26160152). This variant is not present in population databases (ExAC no frequency). This premature translational stop signal has been observed in individual(s) with Leprechaunism (PMID: 16705075). For these reasons, this variant has been classified as Pathogenic. |