Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Genetic Services Laboratory, |
RCV000503966 | SCV000595252 | uncertain significance | not specified | 2016-12-30 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV000765477 | SCV000896768 | uncertain significance | Insulin-resistant diabetes mellitus AND acanthosis nigricans; Hyperinsulinism due to INSR deficiency; Leprechaunism syndrome; Rabson-Mendenhall syndrome | 2018-10-31 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV001302076 | SCV001491269 | uncertain significance | not provided | 2017-06-02 | criteria provided, single submitter | clinical testing | This sequence change replaces aspartic acid with asparagine at codon 1259 of the INSR protein (p.Asp1259Asn). The aspartic acid residue is moderately conserved and there is a small physicochemical difference between aspartic acid and asparagine. This variant is present in population databases (rs369102740, ExAC 0.01%). This variant has not been reported in the literature in individuals with a INSR-related disease. In summary, this variant has uncertain impact on INSR function. The available evidence is currently insufficient to determine its role in disease. Therefore, it has been classified as a Variant of Uncertain Significance. |
Clinical Genomics, |
RCV003884579 | SCV004698148 | uncertain risk allele | Hyperinsulinism due to INSR deficiency | criteria provided, single submitter | research | Potent mutations in INSR gene can lead to insulin resistance, which presents as impaired glucose tolerance, early onset type 2 diabetes, post prandial hyperglycemia and increased insulin requirement in type 1 diabetes. These mutations in INSR gene can also predispose to coronary artery disease, metabolic syndrome, polycystic ovarian disease and non alcoholic fatty liver disease.However, the role of this particular variant rs369102740 with early onset diabetes mellitus is yet to be ascertained. |