Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Labcorp Genetics |
RCV001295723 | SCV001484665 | likely pathogenic | Leukocyte adhesion deficiency 1 | 2022-08-22 | criteria provided, single submitter | clinical testing | In summary, the currently available evidence indicates that the variant is pathogenic, but additional data are needed to prove that conclusively. Therefore, this variant has been classified as Likely Pathogenic. Experimental studies have shown that this missense change affects ITGB2 function (PMID: 11703376). Algorithms developed to predict the effect of missense changes on protein structure and function (SIFT, PolyPhen-2, Align-GVGD) all suggest that this variant is likely to be disruptive. ClinVar contains an entry for this variant (Variation ID: 999697). This missense change has been observed in individual(s) with leukocyte adhesion deficiency type 1 (PMID: 11703376, 22134107, 25703682, 33391282). This variant is present in population databases (rs147318988, gnomAD 0.008%). This sequence change replaces alanine, which is neutral and non-polar, with valine, which is neutral and non-polar, at codon 270 of the ITGB2 protein (p.Ala270Val). |
Gene |
RCV004719127 | SCV005326083 | likely pathogenic | not provided | 2023-09-12 | criteria provided, single submitter | clinical testing | Published functional studies demonstrate a damaging effect on the expression of heterodimers and adhesion of heterodimers to the ligand (Shaw et al., 2001); In silico analysis supports that this missense variant has a deleterious effect on protein structure/function; This variant is associated with the following publications: (PMID: 11703376, 25514840, 11212883, 25703682, 33391282, 29548898, 22134107) |