Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Clin |
RCV001225285 | SCV001397562 | likely pathogenic | Glanzmann thrombasthenia | 2023-05-16 | reviewed by expert panel | curation | The NM_000212.3(ITGB3):c.877C>T variant results in premature termination of translation at Gln293 in exon 6/15. The resulting transcript is predicted to undergo NMD (PVS1). The variant is absent from gnomAD v2.1.1 and v3 (PM2_supporting threshold of <0.0001). The variant is reported in one compound heterozygous individual who does not meet criteria for PP4 (PMID: 30138987). In summary, this variant meets the criteria to be classified as likely pathogenic for autosomal recessive Glanzmann Thrombasthenia based on the ACMG/AMP criteria applied, as specified by the ClinGen PD VCEP: PM2_Supporting, PVS1 (PD VCEP specifications version 2.1). |