Total submissions: 1
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Gene |
RCV000599307 | SCV000709937 | pathogenic | not provided | 2018-01-05 | criteria provided, single submitter | clinical testing | The c.1492_1495delAATG variant in the JAG1 gene has been reported previously in association with Alagille syndrome (Warthen et al., 2006; Oda et al., 1997). The c.1492_1495delAATG variant causes a frameshift starting with codon Asparagine 498, changes this amino acid to a Glycine residue, and creates a premature Stop codon at position 65 of the new reading frame, denoted p.Asn498GlyfsX65. This variant is predicted to cause loss of normal protein function either through protein truncation or nonsense-mediated mRNA decay. The c.1492_1495delAATG variant is not observed in large population cohorts (Lek et al., 2016). We interpret c.1492_1495delAATG as a pathogenic variant. |