Total submissions: 5
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Eurofins Ntd Llc |
RCV000729658 | SCV000857334 | uncertain significance | not provided | 2017-10-04 | criteria provided, single submitter | clinical testing | |
Illumina Laboratory Services, |
RCV001270881 | SCV001451659 | uncertain significance | Alagille syndrome due to a JAG1 point mutation | 2020-06-15 | criteria provided, single submitter | clinical testing | The JAG1 c.5G>T (p.Arg2Leu) variant is a missense variant. A literature search was conducted for the gene, cDNA change, and amino acid change. No publications were identified through this search. This variant is reported at a frequency of 0.000045 in the Total population from the Genome Aggregation Database, though this is based on two alleles in a region of good sequencing coverage in genomes so the variant is presumed to be rare. The arginine at position two is part of the signal peptide domain, which is involved in trafficking of the protein to the correct subcellular location. In silico algorithms differ in their predicted functional consequence of this variant, and its effect has not been investigated experimentally. Based on the limited evidence available, the p.Arg2Leu variant is classified as a variant of uncertain significance for Alagille syndrome. |
Labcorp Genetics |
RCV001270881 | SCV001513941 | benign | Alagille syndrome due to a JAG1 point mutation | 2024-01-07 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002499351 | SCV002806188 | uncertain significance | Alagille syndrome due to a JAG1 point mutation; Tetralogy of Fallot; Deafness, congenital heart defects, and posterior embryotoxon; Charcot-Marie-Tooth disease, axonal, Type 2HH | 2022-02-04 | criteria provided, single submitter | clinical testing | |
Prevention |
RCV004547925 | SCV004113089 | uncertain significance | JAG1-related disorder | 2023-03-08 | criteria provided, single submitter | clinical testing | The JAG1 c.5G>T variant is predicted to result in the amino acid substitution p.Arg2Leu. This variant has been reported in the heterozygous state in an individual with congenital hypogonadotropic hypogonadism (CHH) (Cotellessa L et al. 2023, DOI: 10.1172/jci.insight.161998, https://insight.jci.org/articles/view/161998). This variant is reported in 0.12% (1/866) of alleles in individuals of Latino descent in gnomAD (http://gnomad.broadinstitute.org/variant/20-10654174-C-A). At this time, the clinical significance of this variant is uncertain due to the absence of conclusive functional and genetic evidence. |