Total submissions: 4
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Revvity Omics, |
RCV000003136 | SCV002022618 | likely pathogenic | Palmoplantar keratoderma, epidermolytic | 2021-05-26 | criteria provided, single submitter | clinical testing | |
3billion | RCV000003136 | SCV002058972 | likely pathogenic | Palmoplantar keratoderma, epidermolytic | 2022-01-03 | criteria provided, single submitter | clinical testing | Same nucleotide change resulting in same amino acid change has been previously reported to be associated with KRT9 related disorder (ClinVar ID: VCV000003000, PMID:7512862, PS1_P). The variant is located in a well-established functional domain or exonic hotspot, where pathogenic variants have frequently reported (PM1_M). A different missense change at the same codon has been reported as pathogenic/likely pathogenic with strong evidence (ClinVar ID: VCV000003003, PMID:7523529,7511021,12192490,14675368, PM5_M).T In silico tool predictions suggest damaging effect of the variant on gene or gene product (REVEL: 0.646, 3CNET: 0.992, PP3_P). A missense variant is a common mechanism associated with Palmoplantar keratoderma (PP2_P). It is not observed in the gnomAD v2.1.1 dataset (PM2_M). herefore, this variant is classified as likely pathogenic according to the recommendation of ACMG/AMP guideline. |
OMIM | RCV004562189 | SCV000023294 | pathogenic | Epidermolytic palmoplantar keratoderma, 1 | 2003-07-30 | no assertion criteria provided | literature only | |
Epithelial Biology; Institute of Medical Biology, |
RCV000056463 | SCV000087572 | not provided | not provided | no assertion provided | not provided |