Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000673041 | SCV000798207 | likely pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2C | 2018-03-01 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000673041 | SCV002247247 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2C | 2023-06-20 | criteria provided, single submitter | clinical testing | This sequence change results in a frameshift in the SGCG gene (p.Cys243Leufs*75). While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 49 amino acid(s) of the SGCG protein and extend the protein by 25 additional amino acid residues. This variant is present in population databases (rs758078849, gnomAD 0.007%). This variant has not been reported in the literature in individuals affected with SGCG-related conditions. ClinVar contains an entry for this variant (Variation ID: 556967). For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the SGCG protein in which other variant(s) (p.Pro268Argfs*50) have been determined to be pathogenic (PMID: 8923014). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. |