Total submissions: 2
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Counsyl | RCV000671426 | SCV000796401 | likely pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2C | 2017-12-20 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV000671426 | SCV003461769 | pathogenic | Autosomal recessive limb-girdle muscular dystrophy type 2C | 2023-05-01 | criteria provided, single submitter | clinical testing | For these reasons, this variant has been classified as Pathogenic. This variant disrupts a region of the SGCG protein in which other variant(s) (p.Cys283Tyr) have been determined to be pathogenic (PMID: 10447257, 15322984, 22095924). This suggests that this is a clinically significant region of the protein, and that variants that disrupt it are likely to be disease-causing. This sequence change creates a premature translational stop signal (p.Ser257Alafs*23) in the SGCG gene. While this is not anticipated to result in nonsense mediated decay, it is expected to disrupt the last 35 amino acid(s) of the SGCG protein. This variant is present in population databases (no rsID available, gnomAD 0.006%). This premature translational stop signal has been observed in individual(s) with limb-girdle muscular dystrophy (PMID: 30107846). ClinVar contains an entry for this variant (Variation ID: 555584). |