Total submissions: 3
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Neuberg Centre For Genomic Medicine, |
RCV001823501 | SCV002072984 | likely pathogenic | Hyperlipoproteinemia, type I | criteria provided, single submitter | clinical testing | The missense variant p.G81D in LPL (NM_000237.3) has been reported previously as a pathogenic variant in patients with severe hyperchylomicronemia (Stefanutti et al., 2013; Hegele et al., 2018). The missense variant c.242G>A (p.G81D) in LPL (NM_000237.3) is observed in 1/113558 (0.0009%) alleles from individuals of European (Non-Finnish) background in the gnomAD dataset (Exome Aggregation Consortium et al., 2016), but was not seen in the homozygous state. The p.G81D missense variant is predicted to be damaging by both SIFT and PolyPhen2. The glycine residue at codon 81 of LPL is conserved in all mammalian species. The nucleotide c.242 in LPL is predicted conserved by GERP++ and PhyloP across 100 vertebrates. For these reasons, this variant has been classified as Likely Pathogenic | |
Mendelics | RCV002246536 | SCV002517573 | pathogenic | Hyperlipidemia, familial combined, LPL related | 2022-05-04 | criteria provided, single submitter | clinical testing | |
Ambry Genetics | RCV003299025 | SCV003997137 | likely pathogenic | Cardiovascular phenotype | 2023-05-23 | criteria provided, single submitter | clinical testing | The p.G81D variant (also known as c.242G>A), located in coding exon 2 of the LPL gene, results from a G to A substitution at nucleotide position 242. The glycine at codon 81 is replaced by aspartic acid, an amino acid with similar properties. This alteration has been reported as homozygous and as a compound heterozygote in subjects with features consistent with chylomicronemia syndrome (Stefanutti C et al. Atheroscler Suppl, 2013 Jan;14:73-6; Rabacchi C et al. Atherosclerosis, 2015 Jul;241:79-86; Hegele RA et al. J Clin Lipidol, 2018 Apr;12:920-927.e4). This variant is considered to be rare based on population cohorts in the Genome Aggregation Database (gnomAD). This amino acid position is highly conserved in available vertebrate species. In addition, this alteration is predicted to be deleterious by in silico analysis. Based on the majority of available evidence to date, this variant is likely to be pathogenic. |