Total submissions: 6
Submitter | RCV | SCV | Clinical significance | Condition | Last evaluated | Review status | Method | Comment |
---|---|---|---|---|---|---|---|---|
Ai |
RCV002223759 | SCV002502415 | uncertain significance | not provided | 2021-09-29 | criteria provided, single submitter | clinical testing | |
Fulgent Genetics, |
RCV002490375 | SCV002779995 | uncertain significance | Short QT syndrome type 1; Long QT syndrome 2 | 2021-07-26 | criteria provided, single submitter | clinical testing | |
Labcorp Genetics |
RCV003531903 | SCV004353663 | uncertain significance | Long QT syndrome | 2023-01-01 | criteria provided, single submitter | clinical testing | In summary, the available evidence is currently insufficient to determine the role of this variant in disease. Therefore, it has been classified as a Variant of Uncertain Significance. Experimental studies have shown that this missense change affects KCNH2 function (PMID: 24204727, 25417810). Algorithms developed to predict the effect of missense changes on protein structure and function are either unavailable or do not agree on the potential impact of this missense change (SIFT: "Deleterious"; PolyPhen-2: "Probably Damaging"; Align-GVGD: "Class C15"). ClinVar contains an entry for this variant (Variation ID: 14440). This missense change has been observed in individual(s) with long QT syndrome (PMID: 11854117, 15051636). This variant is not present in population databases (gnomAD no frequency). This sequence change replaces asparagine, which is neutral and polar, with isoleucine, which is neutral and non-polar, at codon 861 of the KCNH2 protein (p.Asn861Ile). |
OMIM | RCV000015522 | SCV000035787 | pathogenic | Long QT syndrome 2 | 2004-04-20 | no assertion criteria provided | literature only | |
OMIM | RCV000015523 | SCV000035788 | pathogenic | Long QT syndrome 2/5, digenic | 2004-04-20 | no assertion criteria provided | literature only | |
Cardiovascular Biomedical Research Unit, |
RCV000058141 | SCV000089661 | not provided | Congenital long QT syndrome | no assertion provided | literature only | This variant has been reported as associated with Long QT syndrome in the following publications (PMID:10973849;PMID:11854117;PMID:15051636). This is a literature report, and does not necessarily reflect the clinical interpretation of the Imperial College / Royal Brompton Cardiovascular Genetics laboratory. |